stella
Cystic FibrosisSeptember 2021

What Researchers Found in the Long-Term Lumacaftor-Ivacaftor Study for Young Children

This extension study followed 57 children ages 2-5 with cystic fibrosis homozygous for the F508del mutation on lumacaftor-ivacaftor for up to 96 weeks. The drug was generally safe, and gains in sweat chloride, growth, and pancreatic function held up.

What the trial was testing

The trial enrolled 57 patients with cystic fibrosis. The study was sponsored by Vertex Pharmaceuticals and tracked outcomes across the full group of patients who matched the trial's eligibility profile.

It was a large trial designed to confirm whether the treatment works well enough for wider use. Trials at this stage are designed to produce evidence regulators and physicians can act on — not just observations to follow up later.

What the results showed

Sweat chloride dropped 29.6 mmol/L on lumacaftor-ivacaftor and stayed lower.

The Lancet Respiratory Medicine · 2021 · NCT03125395

These findings — that in sweat chloride sustained over 96 weeks on lumacaftor-ivacaftor in young children — were published in the The Lancet Respiratory Medicine and represent the headline result of the study.

Researchers tracked outcomes across 57 patients enrolled in the trial. The result was consistent enough across the group that the team felt confident reporting it.

What this means for patients

For patients with cystic fibrosis, this result changes the calculus on what to ask their care team about. Whether it changes day-to-day care depends on factors like disease subtype, prior treatments, and where the patient is in their care journey.

What you can do now

Lumacaftor-ivacaftor (Orkambi) is FDA-approved and available now for children 1 and older with two F508del mutations. However, most CF clinics now use the newer triple combo (Trikafta) when eligible since it works better. Ask your CF team which CFTR modulator is best for your child's genotype and age.

Eligibility for the treatments mentioned above depends on specific test results and clinical history. Bring this summary, the trial name, and your most recent labs or pathology report to your next visit.